نتایج جستجو برای: dominant mutation

تعداد نتایج: 404478  

Journal: :Arteriosclerosis, thrombosis, and vascular biology 2015
Angelo B Cefalù Rossella Spina Davide Noto Vincenza Valenti Valeria Ingrassia Antonina Giammanco Maria D Panno Antonina Ganci Carlo M Barbagallo Maurizio R Averna

OBJECTIVE Cyclic AMP responsive element-binding protein 3-like 3 (CREB3L3) is a novel candidate gene for dominant hypertriglyceridemia. To date, only 4 kindred with dominant hypertriglyceridemia have been found to be carriers of 2 nonsense mutations in CREB3L3 gene (245fs and W46X). We investigated a family in which hypertriglyceridemia displayed an autosomal dominant pattern of inheritance. ...

2015
Thomas M. Bennett Donna S. Mackay Harry L.S. Knopf Alan Shiels

A novel missense mutation in the gene for gap-junction protein α3 (GJA3) associated with autosomal dominant " nuclear punctate " cataracts linked to chromosome 13qA novel missense mutation in the gene for gap-junction protein α3 (GJA3) associated with autosomal dominant " nuclear punctate " cataracts linked to chromosome 13q.

Journal: :Movement disorders : official journal of the Movement Disorder Society 2004
Akio Kikuchi Atsushi Takeda Kazuo Fujihara Teiko Kimpara Yusei Shiga Hiroaki Tanji Makiko Nagai Hiroshi Ichinose Fumi Urano Nobuyuki Okamura Hiroyuki Arai Yasuto Itoyama

We describe a 54-year-old man with dominant adult-onset dopa-responsive dystonia (DRD) with parkinsonism caused by an Arg184His mutation in guanosine 5'-triphosphate cyclohydrolase I (GCH-I). This is the first mutation in the GCH-I gene that has been proven to be responsible for both recessive and dominant phenotypes.

Journal: :Journal of virology 1992
C M Bentivoglio J Zhu C N Cole

Mutations at multiple sites within the simian virus 40 (SV40) early region yield large T antigens which interfere trans dominantly with the replicative activities of wild-type T antigen. A series of experiments were conducted to study possible mechanisms of interference with SV40 DNA replication caused by these mutant T antigens. First, the levels of wild-type T antigen expression in cells cotr...

Journal: :Human molecular genetics 1999
G Sjöberg C A Saavedra-Matiz D R Rosen E M Wijsman K Borg S H Horowitz T Sejersen

In some myopathies of distal onset, the intermediate filament desmin is abnormally accumulated in skeletal and cardiac muscle. We report the first point mutation in desmin cosegregating with an autosomal dominant form of desmin-related myopathy. The L345P desmin missense mutation occurs in a large, six generation Ashkenazi Jewish family. The mutation is located in an evolutionarily highly conse...

Background Neurofibromatosis is an autosomal dominant disease. It affects one in 2,700 to 3,300 people. The main gene mutated in the disease is a tumor suppressor protein called neurofibromin. There are several categories, the most important of which is divided into two types of type I and type 2 neurofibromatosis. Here, we aimed to identify th...

Journal: :Movement disorders : official journal of the Movement Disorder Society 2012
Maya Ando Manabu Funayama Yuanzhe Li Kenichi Kashihara Yoshitake Murakami Nobutaka Ishizu Chizuko Toyoda Katsuhiko Noguchi Takashi Hashimoto Naoki Nakano Ryogen Sasaki Yasumasa Kokubo Shigeki Kuzuhara Kotaro Ogaki Chikara Yamashita Hiroyo Yoshino Taku Hatano Hiroyuki Tomiyama Nobutaka Hattori

Vacuolar protein sorting 35 (VPS35) was recently reported to be a pathogenic gene for late-onset autosomal dominant Parkinson's disease (PD), using exome sequencing. To date, VPS35 mutations have been detected only in whites with PD. The aim of the present study was to determine the incidence and clinical features of Asian PD patients with VPS35 mutations. We screened 7 reported nonsynonymous m...

Journal: :Hong Kong medical journal = Xianggang yi xue za zhi 2009
K Y Chan C K Ching Chloe M Mak C W Lam Albert Y W Chan

Hereditary spastic paraplegias are a heterogeneous group of chronic central motor system disorders, characterised by progressive lower limb spasticity. Hereditary spastic paraplegia is clinically classified into pure and complicated forms, by the absence or presence of additional neurological or extra-neurological features. Hereditary spastic paraplegias follow all modes of inheritance and the ...

Journal: :Children (Basel) 2023

Sotos syndrome is an autosomal dominant genetic disorder caused by mutations in the NSD1 gene. In this study, we report a case of preterm infant. The main clinical manifestations were severe bronchopulmonary dysplasia, congenital heart disease, difficulty feeding, and characteristic facial appearance. gene mutation was located at 177251854 on chromosome 5, identified as shear mutation, c.4765+1...

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