نتایج جستجو برای: wolfram syndrome

تعداد نتایج: 623455  

جعفری, عبدالحمید, خیراندیش, مریم, دهقانی, خدیجه, متوسلیان, فاطمه, نورانی, فروغ السادات, هاشمی, اعظم السادات,

Thiamine Responsive megaloblastic anemia in DIDMOA (Wolfram) syndrome has an autosomal- recessive mode of inheritance . Megaloblastic anemia and sideroblastic anemia is accompanied by diabetes insipidus (DI), diabetes mellitus (DM) ,optic atrophy (OA) and deafness (D). Neutropenia and thrombocytopenia are also present. We report a 7 month old girl with congenital macrocytic anemia a rare clin...

Journal: :Archivos argentinos de pediatria 2016
Hüseyin A Korkmaz Korcan Demir Filiz Hazan Melek Yıldız Özlem N Elmas Behzat Özkan

Wolfram syndrome (DIDMOAD: diabetes insipidus, diabetes mellitus, optic atrophy and deafness) is a rare neurodegenerative disorder. Mutations of the WFS1 (wolframin) on chromosome 4 are responsible for the clinical manifestations in majority of patients with Wolfram syndrome. Wolfram syndrome is also accompanied by neurologic and psychiatric disorders, urodynamic abnormalities, restricted joint...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2014
Simin Lu Kohsuke Kanekura Takashi Hara Jana Mahadevan Larry D Spears Christine M Oslowski Rita Martinez Mayu Yamazaki-Inoue Masashi Toyoda Amber Neilson Patrick Blanner Cris M Brown Clay F Semenkovich Bess A Marshall Tamara Hershey Akihiro Umezawa Peter A Greer Fumihiko Urano

Wolfram syndrome is a genetic disorder characterized by diabetes and neurodegeneration and considered as an endoplasmic reticulum (ER) disease. Despite the underlying importance of ER dysfunction in Wolfram syndrome and the identification of two causative genes, Wolfram syndrome 1 (WFS1) and Wolfram syndrome 2 (WFS2), a molecular mechanism linking the ER to death of neurons and β cells has not ...

Journal: :مجله دانشگاه علوم پزشکی شهید صدوقی یزد 0
اعظم السادات هاشمی a hashemi . [email protected] عبدالحمید جعفری ah jafari مریم خیراندیش m kheirandish خدیجه دهقانی kh dehghani فروغ السادات نورانی f nourani فاطمه متوسلیان f motavaselian

thiamine responsive megaloblastic anemia in didmoa (wolfram) syndrome has an autosomal- recessive mode of inheritance . megaloblastic anemia and sideroblastic anemia is accompanied by diabetes insipidus (di), diabetes mellitus (dm) ,optic atrophy (oa) and deafness (d). neutropenia and thrombocytopenia are also present. we report a 7 month old girl with congenital macrocytic anemia a rare clinic...

2016
Fumihiko Urano

Wolfram syndrome is a rare genetic disorder characterized by juvenile-onset diabetes mellitus, diabetes insipidus, optic nerve atrophy, hearing loss, and neurodegeneration. Although there are currently no effective treatments that can delay or reverse the progression of Wolfram syndrome, the use of careful clinical monitoring and supportive care can help relieve the suffering of patients and im...

Journal: :Neurology: Clinical Practice 2019

2014
Linshan Shang Haiqing Hua Kylie Foo Hector Martinez Kazuhisa Watanabe Matthew Zimmer David J. Kahler Matthew Freeby Wendy Chung Charles LeDuc Robin Goland Rudolph L. Leibel Dieter Egli

Wolfram syndrome is an autosomal recessive disorder caused by mutations in WFS1 and is characterized by insulin-dependent diabetes mellitus, optic atrophy, and deafness. To investigate the cause of β-cell failure, we used induced pluripotent stem cells to create insulin-producing cells from individuals with Wolfram syndrome. WFS1-deficient β-cells showed increased levels of endoplasmic reticulu...

Journal: :The Journal of the Association of Physicians of India 1978
V Viswanathan S Medempudi M Kadiri

Wolfram syndrome is a rare neurodegenerative and genetic disorder, which should be suspected in patients with young onset non-immune insulin dependent diabetes mellitus and optic atrophy. Patients are most likely to develop diabetes insipidus, deafness, urinary tract, and neurological abnormalities. 60% of the people with Wolfram syndrome die at age 35, usually due to central respiratory center...

Journal: :iranian journal of public health 0
ensieh nasli esfahani maryam ghodsi ali tootee camelia rambod bagher larijani akbar soltani

background: cell therapy has emerged as a promising curative intervention for several diseases including diabetes and wolfram syndrome (ws). the current study aimed to assess the effectiveness of clinical application of fetal-liver derived stem cells for treatment of patients with ws. methods: six patients with ws aged 23-34 (mean: 29.50, sd: 4.76) were recruited for the current phase 3 single-...

Journal: :Jornal de pediatria 2002
Paulo R G Zen Louise L C Pinto Ida V D Schwartz Timothy G Barrett Giorgio Paskulin

OBJECTIVE To report a case of a patient diagnosed with Wolfram Syndrome and brachydactyly type E. Wolfram Syndrome is characterized by the presence of diabetes mellitus, diabetes insipidus, atrophy of the optic nerve, alterations of the urinary tract, deafness and neurologic and psychiatric disorders. However, not all manifestations are present at diagnosis, indicating the necessity of long-ter...

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